Acute supporative osteomyelitis of the lower jaw in Wolfram syndrome: Report of case and review of literature | Health & Environmental Research Online (HERO)

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Citation
Tags

HERO ID

576202

Reference Type

Journal Article

Subtype

Review

Title

Acute supporative osteomyelitis of the lower jaw in Wolfram syndrome: Report of case and review of literature

Author(s)

Mortazavi, H; Shahoon, H; Khojasteh, A

Year

2005

Is Peer Reviewed?

Journal

Oral Oncology Extra
ISSN: 1741-9409

Volume

Issue

Page Numbers

191-194

DOI

10.1016/j.ooe.2005.05.005

Abstract

Summary Wolfram syndrome is a rare, congenital, multisystem disorder believed to be caused by both mitochondrial and nuclear gene dysfunction. Diabetes insipidus, diabetes mellitus, and vision and hearing defects are the main symptoms associated with this syndrome. Disorders of the urinary tract are also often present. Wolfram syndrome affects males and females equally and may be inherited as an autosomal recessive trait. Here in we report a patient with acute supporative osteomyelitis who suffered from wolfram syndrome. Correction of the baseline ketoacidotic situation and aggressive antiobiotic therapy lead to complete healing of the lesion.

Keywords

Wolfram; Diabete; Osteomyelytis; Syndrome